Overview

Definition:
-An adrenal incidentaloma is an adrenal mass discovered incidentally during imaging performed for reasons unrelated to suspected adrenal pathology
-In adolescents, it is crucial to differentiate between benign adenomas and potentially malignant or hormonally active tumors, requiring a targeted hormonal workup.
Epidemiology:
-Adrenal incidentalomas are less common in children and adolescents compared to adults, with prevalence estimates varying
-Malignant tumors and functioning adenomas are relatively more common in younger populations
-Incidence increases with age.
Clinical Significance:
-Untreated hormonally active adrenal incidentalomas can lead to significant morbidity and mortality, including hypertension, hypokalemia, diabetes mellitus, growth disturbances, and even adrenal crisis
-Differentiating benign from malignant lesions is critical for appropriate management and prognosis in adolescents.

Clinical Presentation

Symptoms:
-Often asymptomatic
-However, symptoms may arise from hormonal overproduction: Hypertension, hypokalemia, muscle weakness, fatigue, unexplained weight gain or loss, abdominal striae, hirsutism, virilization, menstrual irregularities, emotional lability, polyuria, polydipsia.
Signs:
-Hypertension, hypokalemia (serum K+ < 3.5 mmol/L), Cushingoid features (moon facies, central obesity, thin skin, striae), signs of virilization (clitoromegaly, hirsutism), goiter
-In rare cases, palpable abdominal mass.
Diagnostic Criteria:
-Diagnosis is based on incidental finding of an adrenal mass on imaging
-The subsequent hormonal workup aims to detect autonomous hormone production or malignancy.

Diagnostic Approach

History Taking:
-Detailed family history of endocrine tumors or hypertension
-History of rapid weight gain/loss, fatigue, increased thirst/urination, menstrual irregularities, signs of precocious puberty, palpitations, headaches, sweating
-Medications, especially steroids.
Physical Examination:
-Thorough assessment of blood pressure, BMI, and presence of Cushingoid features, virilization, or other endocrine stigmata
-Palpation for abdominal masses
-Careful examination of skin for striae and pigmentation.
Investigations:
-Initial screening tests include: 1
-Overnight low-dose dexamethasone suppression test (LDDST) for Cushing's syndrome (plasma cortisol > 1.8 mcg/dL or 50 nmol/L after 1 mg dexamethasone at midnight is suspicious)
-2
-24-hour urinary fractionated metanephrines and normetanephrines for pheochromocytoma (elevated levels indicate suspicion)
-3
-Plasma renin activity and plasma aldosterone concentration with the aldosterone-to-renin ratio (ARR) for primary hyperaldosteronism (a ratio > 20-30 with suppressed plasma renin activity is suggestive, but further confirmation is needed)
-4
-Serum potassium levels (hypokalemia may suggest hyperaldosteronism or pheochromocytoma)
-Imaging (CT/MRI) provides morphological information but hormonal workup is key for functional assessment
-Size > 4 cm, irregular borders, heterogeneity, and rapid growth on repeat imaging suggest malignancy but do not replace hormonal evaluation.
Differential Diagnosis: Benign adrenal adenoma (non-functioning), adrenal carcinoma, pheochromocytoma, Cushing's syndrome (adenoma, hyperplasia, or ectopic ACTH), primary hyperaldosteronism, congenital adrenal hyperplasia variants, adrenal metastasis, adrenal cyst, adrenal hemorrhage.

Management

Initial Management:
-The primary goal is to rule out clinically significant hormone hypersecretion and malignancy
-Initial management focuses on targeted hormonal screening based on clinical suspicion and imaging characteristics
-Size thresholds for further investigation are debated but generally >2 cm or growing lesions warrant more thorough assessment.
Medical Management:
-If a specific hormone excess is confirmed: Cushing's syndrome: Medical therapy with ketoconazole, metyrapone, or osilodrostat
-Pheochromocytoma: Alpha-adrenergic blockade (e.g., prazosin, terazosin) followed by beta-adrenergic blockade (e.g., propranolol) if tachyarrhythmias are present
-Primary hyperaldosteronism: Aldosterone antagonists like spironolactone or eplerenone.
Surgical Management:
-Surgical excision (adrenalectomy) is indicated for: 1
-Confirmed significant hormone hypersecretion (Cushing's syndrome, pheochromocytoma, primary hyperaldosteronism resistant to medical therapy or causing severe complications)
-2
-Suspected or confirmed adrenal malignancy (based on imaging or biopsy)
-3
-Lesions > 4-6 cm, irrespective of hormonal activity, due to higher risk of malignancy
-Laparoscopic adrenalectomy is the preferred approach for benign lesions.
Supportive Care:
-Monitoring of blood pressure, electrolytes, and glucose levels
-Nutritional support tailored to hormonal status
-Psychosocial support for adolescents and families dealing with diagnosis and treatment.

Complications

Early Complications:
-Perioperative complications of adrenalectomy: bleeding, infection, adrenal crisis (especially if bilateral adrenalectomy or significant hypothalamic-pituitary axis suppression)
-Hypertensive crisis during pheochromocytoma manipulation
-Electrolyte imbalances.
Late Complications:
-Recurrence of hormone hypersecretion if resection is incomplete or if multifocal disease
-Development of contralateral adrenal adenoma
-Growth impairment or metabolic sequelae from prolonged hormone excess
-Metastasis in cases of adrenal carcinoma.
Prevention Strategies:
-Adequate pre-operative blockade for pheochromocytoma
-Careful intraoperative technique to minimize bleeding and damage
-Appropriate post-operative hormonal replacement if needed
-Thorough follow-up to detect recurrence or new lesions.

Prognosis

Factors Affecting Prognosis:
-Tumor type (benign vs
-malignant), degree of hormone hypersecretion, presence of metastasis, promptness and efficacy of treatment, and patient's overall health status
-For benign adenomas with appropriate management, prognosis is generally excellent.
Outcomes:
-Successful treatment of hormone-secreting tumors leads to normalization of biochemical parameters and improvement in clinical symptoms
-Complete resection of adrenal carcinoma offers the best chance of cure but is often challenging
-Surveillance is crucial for all patients.
Follow Up:
-Regular clinical evaluations, blood pressure monitoring, and biochemical tests (hormonal assays) are essential
-Imaging surveillance (CT/MRI) may be required depending on the initial diagnosis, especially for larger or suspicious lesions, and for adrenal carcinoma to monitor for recurrence or metastasis.

Key Points

Exam Focus:
-Distinguish between functioning and non-functioning incidentalomas
-Remember screening tests for Cushing's, pheochromocytoma, and hyperaldosteronism
-Understand indications for surgery vs
-medical management
-Adrenal crisis prevention post-adrenalectomy.
Clinical Pearls:
-Always consider the possibility of a functioning tumor even in asymptomatic adolescents with incidentalomas
-Aggressively investigate masses >4 cm or those with suspicious imaging features
-For suspected pheochromocytoma, alpha-blockade MUST precede beta-blockade.
Common Mistakes:
-Failing to perform adequate hormonal workup for incidentalomas
-Initiating beta-blockers before alpha-blockers in suspected pheochromocytoma
-Inadequate follow-up leading to missed recurrence or complications
-Assuming all incidentalomas are benign adenomas.