Overview

Definition:
-Atlantoaxial instability (AAI) refers to excessive movement between the first two cervical vertebrae (atlas and axis), potentially leading to spinal cord compression
-In Down syndrome (DS), this is due to ligamentous laxity and structural abnormalities of the craniovertebral junction.
Epidemiology:
-AAI is found in approximately 10-30% of individuals with Down syndrome, although symptomatic AAI is much less common, occurring in about 1-2%
-The prevalence increases with age and is more commonly associated with specific vertebral anomalies.
Clinical Significance:
-Untreated symptomatic AAI can lead to serious neurological deficits, including myelopathy, quadriplegia, and even death
-Early identification and management are crucial for preventing irreversible neurological damage and ensuring optimal quality of life for individuals with DS.

Clinical Presentation

Symptoms:
-Many individuals with AAI are asymptomatic
-When symptoms occur, they can be subtle and progressive: Neck pain or stiffness
-Occipital headache
-Changes in gait, such as spasticity or ataxia
-Upper extremity weakness or paresthesias
-Lower extremity spasticity
-Changes in bowel or bladder function (rare in early stages)
-Torticollis (head tilt).
Signs:
-Neurological examination may reveal: Spasticity in the lower extremities
-Hyperreflexia
-Clonus
-Positive Babinski sign
-Impaired proprioception
-Limited neck range of motion
-Tenderness to palpation over the upper cervical spine.
Diagnostic Criteria:
-There are no universally agreed-upon diagnostic criteria for asymptomatic AAI screening
-However, instability is generally defined by radiographic measurements: Increased atlanto-dental interval (ADI) >5 mm in children and >3 mm in adults
-Dynamic radiographic views (flexion-extension) showing >5 mm of displacement
-Other parameters include posterior displacement of the atlas and sagittal malalignment of the craniocervical junction.

Screening Controversies

Current Recommendations:
-Historically, routine screening with radiographs was recommended for all children with DS
-However, recent guidelines from organizations like the American Academy of Pediatrics (AAP) and the Centers for Disease Control and Prevention (CDC) have shifted away from universal routine screening due to low yield of symptomatic cases and potential radiation exposure.
Arguments For Screening:
-Proponents argue that identifying asymptomatic instability allows for proactive management and prevention of neurological injury
-Early detection can prevent irreversible damage
-Some advocate for screening at specific ages or in children with concerning symptoms.
Arguments Against Screening:
-Opponents highlight the low incidence of symptomatic AAI, the risk of radiation from X-rays, and the high rate of false positives
-They emphasize that most individuals with DS and AAI remain asymptomatic throughout life
-The focus is shifting towards clinical monitoring and selective screening.
Risk Stratification:
-Current approaches often involve risk stratification, identifying individuals with DS who may benefit more from screening based on clinical signs or specific vertebral anomalies
-This includes children with symptoms of neurological compromise or those with known structural abnormalities.

Diagnostic Approach

History Taking:
-Detailed history focusing on neurological symptoms: gait disturbances, neck pain, headache, motor skill regression, changes in tone, bowel/bladder issues
-Family history of AAI or neurological conditions
-Previous injuries.
Physical Examination:
-Thorough neurological exam: assess gait, tone, reflexes, coordination, cranial nerves, and sensory pathways
-Assess neck ROM and palpate for tenderness
-Look for signs of torticollis.
Investigations:
-Radiographs of the cervical spine in neutral, flexion, and extension views are standard for assessing ADI and dynamic instability
-MRI of the craniovertebral junction is preferred for detailed evaluation of spinal cord compression, ligamentous integrity, and bony abnormalities, especially if neurological symptoms are present or suspicion is high
-CT may be used for detailed bony assessment.
Differential Diagnosis:
-Other causes of neurological symptoms in children with DS: congenital heart disease, hearing loss, thyroid dysfunction, developmental delays, peripheral neuropathy, atlanto-occipital dislocation (rare)
-Neurological symptoms can also be nonspecific and related to other conditions.

Management

Initial Management:
-For asymptomatic AAI: conservative management with activity modification (avoiding contact sports, high-impact activities, and hyperflexion/hyperextension of the neck)
-Regular clinical monitoring and periodic radiographic assessment may be considered based on risk factors and clinical judgment.
Medical Management:
-No specific medical management for the instability itself
-Focus is on symptom relief if present (e.g., pain management)
-Bracing is generally not effective for AAI in DS.
Surgical Management:
-Surgery is indicated for symptomatic AAI or asymptomatic AAI with significant radiological findings (e.g., marked instability or evidence of cord compression)
-Surgical goals include decompression and stabilization (e.g., posterior fixation)
-Indications are carefully individualized.
Supportive Care:
-Education of parents and caregivers regarding activity restrictions
-Regular follow-up with specialists (pediatrician, neurologist, orthopedist)
-Early referral to physical and occupational therapy if neurological deficits are present.

Prognosis

Factors Affecting Prognosis:
-The prognosis for individuals with AAI in DS depends on whether it becomes symptomatic and the extent of neurological compromise
-Early diagnosis and appropriate management, including surgical intervention when necessary, lead to better outcomes
-Aggressive activity can worsen prognosis.
Outcomes:
-Most individuals with asymptomatic AAI remain so throughout life
-Those who develop symptoms and are treated appropriately can have stable neurological function
-Severe myelopathy can lead to permanent disability, but this is uncommon with vigilant care.
Follow Up:
-Long-term follow-up is essential, especially for those with known AAI or a history of instability
-This includes regular clinical assessments and potentially periodic imaging, tailored to the individual's risk profile and symptoms
-Lifelong awareness is important.

Key Points

Exam Focus:
-Understand the controversy surrounding routine screening vs
-selective screening
-Know the typical radiographic findings (ADI >5mm in children)
-Recognize that symptomatic AAI is less common than radiographic AAI
-Management is primarily conservative for asymptomatic cases, with surgery for symptomatic or severe instability.
Clinical Pearls:
-Always consider AAI in the differential diagnosis of new neurological signs or symptoms in a child with Down syndrome
-Emphasize activity modification for children with known AAI, even if asymptomatic
-Recognize that "normal" ADI varies with age and flexion/extension.
Common Mistakes:
-Over-reliance on routine radiography without considering clinical signs
-Undertreating symptomatic AAI due to fear of surgery
-Recommending aggressive sports for individuals with known AAI
-Neglecting to re-evaluate symptoms or radiographic findings over time.