Overview

Definition: Hirschsprung disease (congenital aganglionic megacolon) is a congenital disorder characterized by the absence of ganglion cells in the myenteric (Auerbach) and submucosal (Meissner) plexuses of a segment of the colon, leading to functional obstruction.
Epidemiology:
-It affects approximately 1 in 5000 live births
-The male-to-female ratio is approximately 4:1
-Associated with genetic syndromes such as Down syndrome (trisomy 21) in up to 10% of cases.
Clinical Significance:
-Hirschsprung disease is a critical cause of neonatal intestinal obstruction and requires prompt diagnosis and surgical management to prevent life-threatening complications like enterocolitis and sepsis
-Understanding its pathophysiology and management is crucial for pediatricians and surgeons preparing for DNB and NEET SS exams.

Clinical Presentation

Symptoms:
-Failure to pass meconium within 24-48 hours of birth
-Abdominal distension
-Bilious vomiting
-Constipation
-Poor feeding
-Growth failure
-Explosive stools after digital stimulation
-Palpable fecal mass
-Rectal examination may reveal an empty rectum with a tight anal sphincter and, upon withdrawal, a forceful expulsion of gas and stool (squirt sign or blast sign).
Signs:
-Abdominal distension
-Visible bowel loops
-Tenderness
-Fever (suggestive of enterocolitis).
Diagnostic Criteria:
-Diagnosis is primarily based on a combination of clinical suspicion, radiological findings, and definitive histological confirmation of absent ganglion cells in a full-thickness rectal biopsy
-Genetic testing may be considered in suspected syndromic cases.

Diagnostic Approach

History Taking:
-Detailed birth history (gestational age, events)
-Feeding history and weight gain
-Bowel habit history (frequency, consistency, difficulty with defecation)
-Any episodes of vomiting or abdominal distension
-Family history of Hirschsprung disease or other gastrointestinal anomalies.
Physical Examination:
-General assessment of hydration and distress
-Abdominal examination for distension, tenderness, palpable masses, and bowel sounds
-Digital rectal examination to assess anal tone, rectal vault emptiness, and presence of the squirt sign.
Investigations:
-Abdominal X-ray: May show dilated loops of bowel proximal to an aganglionic segment and a narrow distal segment, but often non-specific
-Contrast enema (barium or water-soluble contrast): Shows a narrowed distal aganglionic segment with dilated proximal bowel and an abrupt transition zone
-Rectal manometry: Assesses anal sphincter relaxation response to rectal distension (normally present
-absent in Hirschsprung disease)
-Rectal biopsy (full-thickness or suction): Gold standard for diagnosis
-demonstrates absence of ganglion cells in the submucosal and myenteric plexuses and presence of hypertrophied nerve fibers
-Biopsy should be taken from adequate depth to include the submucosa.
Differential Diagnosis:
-Meconium ileus (often associated with cystic fibrosis)
-Intestinal atresia or stenosis
-Malrotation with volvulus
-Intestinal duplication cysts
-Functional constipation
-Imperforate anus.

Management

Initial Management:
-If suspected neonatally, immediate decompression of the abdomen with a rectal tube or nasogastric tube
-Fluid and electrolyte management
-Antibiotics if enterocolitis is suspected.
Surgical Management:
-Definitive treatment is surgical
-The goal is to resect the aganglionic bowel and restore bowel continuity by connecting the normally innervated bowel to the anus
-Procedures include: 1
-Swenson pull-through: Total colectomy with rectosigmoid resection and coloanal anastomosis
-2
-Soave endorectal pull-through: Aganglionic mucosa is dissected off the muscularis externa, and normally innervated bowel is pulled through the muscular sleeve and anastomosed to the anus
-3
-Duhamel pull-through: Posterior rectosigmoid resection with a side-to-side pull-through anastomosis of the ganglionic bowel to the anus, leaving the muscular cuff of the aganglionic segment
-A temporary diverting colostomy is often performed in neonates to decompress the bowel and allow for bowel preparation before the pull-through procedure.
Supportive Care:
-Postoperative care involves pain management, intravenous fluids, gradual reintroduction of oral feeds, and monitoring for complications such as anastomotic leak, infection, and enterocolitis
-Long-term management may include bowel irrigation and stool softeners.

Complications

Early Complications:
-Anastomotic leak
-Wound infection
-Sepsis
-Enterocolitis (can be life-threatening)
-Bowel obstruction
-Stenosis at the anastomosis.
Late Complications:
-Persistent constipation or encopresis
-Recurrent enterocolitis
-Rectal prolapse
-Sexual dysfunction
-Stricture formation at the anastomosis.
Prevention Strategies:
-Adequate bowel preparation before pull-through surgery
-Careful surgical technique to ensure complete resection of aganglionic bowel and a tension-free anastomosis
-Prompt recognition and management of enterocolitis
-Appropriate postoperative care and follow-up.

Prognosis

Factors Affecting Prognosis:
-Length of the aganglionic segment (shorter segment generally has better outcomes)
-Presence of associated anomalies or syndromes (e.g., Down syndrome)
-Promptness and adequacy of surgical treatment
-Management of postoperative complications, particularly enterocolitis
-Quality of postoperative care and follow-up.
Outcomes:
-With timely diagnosis and surgical intervention, most children achieve satisfactory bowel control and good quality of life
-However, some may experience chronic constipation, soiling, or recurrent enterocolitis
-The success rates of pull-through procedures are generally high, with over 90% of patients achieving good to excellent functional results.
Follow Up:
-Regular follow-up is essential to monitor bowel function, detect early signs of complications (especially enterocolitis and anastomotic strictures), and provide ongoing support for bowel management
-This includes physical examinations, assessment of bowel habits, and periodic rectal irrigations if needed.

Key Points

Exam Focus:
-The definition and pathophysiology of Hirschsprung disease (absence of ganglion cells)
-The diagnostic triad: clinical suspicion, contrast enema findings (transition zone), and rectal biopsy confirmation (gold standard)
-Common surgical procedures (Swenson, Soave, Duhamel) and the role of a diverting colostomy
-Management of enterocolitis as a critical complication.
Clinical Pearls:
-Always consider Hirschsprung disease in a neonate failing to pass meconium
-Rectal biopsy must be full-thickness and include submucosa
-The squirt sign is a helpful bedside clue
-Enterocolitis is a surgical emergency requiring prompt decompression and antibiotics.
Common Mistakes:
-Inadequate rectal biopsy technique leading to false-negative results
-Delaying surgery in symptomatic neonates
-Inadequate bowel preparation before pull-through
-Underestimating the severity and risk of enterocolitis
-Failing to counsel parents about potential long-term bowel management challenges.