Overview

Definition:
-Severe Combined Immunodeficiency (SCID) refers to a group of rare, inherited genetic disorders characterized by profound defects in both T-cell and B-cell mediated immunity, leading to a severely compromised immune system
-Infants with SCID are highly susceptible to opportunistic infections from bacteria, viruses, and fungi, and often do not survive their first year of life without intervention.
Epidemiology:
-SCID affects approximately 1 in 58,000 live births worldwide
-The incidence varies slightly by population and genetic background
-In India, while specific large-scale screening data is emerging, the global incidence suggests a significant number of affected infants born annually.
Clinical Significance:
-Early diagnosis and prompt treatment are critical for SCID
-Without intervention, infants develop recurrent, severe infections that can be life-threatening
-Newborn screening (NBS) has become a cornerstone for identifying affected infants before they become symptomatic, allowing for timely referral and definitive management, most commonly hematopoietic stem cell transplantation (HSCT) or gene therapy
-Protective isolation is crucial for preventing life-threatening infections in infants awaiting diagnosis or definitive treatment.

Clinical Presentation

Symptoms:
-Failure to thrive
-Recurrent, severe, and persistent infections, including pneumonia, sepsis, diarrhea, skin infections, and oral thrush that does not respond to standard treatment
-Opportunistic infections are common
-Lymphadenopathy and tonsillar hypertrophy are typically absent due to the T-cell defect.
Signs:
-Generalized lymphopenia, specifically T-cell deficiency
-Absence of lymphoid tissue (thymus, lymph nodes, tonsils) on imaging
-Normal or elevated absolute lymphocyte count (ALC) can be misleading
-enumeration of lymphocyte subsets is key
-Presence of severe infections despite appropriate antibiotic therapy.
Diagnostic Criteria:
-Confirmed SCID diagnosis relies on laboratory confirmation of severely impaired T-cell receptor excision circle (TREC) levels, absent or severely reduced T-cell numbers, and absent or significantly impaired B-cell function (low or absent immunoglobulins, poor response to vaccines)
-Genetic testing confirms the specific gene mutation responsible for the SCID phenotype.

Diagnostic Approach

History Taking:
-Detailed birth history including any consanguinity
-Family history of infant deaths, recurrent infections, or known primary immunodeficiencies
-Detailed history of infant's health: feeding patterns, number and type of infections, response to prior treatments, vaccination status (which are often contraindicated if SCID is suspected)
-Red flags include persistent thrush, severe diarrhea, pneumonia, or sepsis unresponsive to antibiotics.
Physical Examination:
-Thorough physical examination focusing on signs of infection
-Palpate for lymphadenopathy and check for tonsils
-Assess skin for signs of infection
-Evaluate for failure to thrive
-Absence of palpable lymph nodes or tonsils in a young infant should raise suspicion for SCID.
Investigations:
-Initial screening: TREC analysis (via dried blood spot) for T-cell lymphopenia
-Confirmation: Complete blood count with differential, lymphocyte subset analysis (CD3, CD4, CD8, CD19, CD56), serum immunoglobulin levels (IgG, IgA, IgM), and specific antibody responses to vaccinations (e.g., tetanus, pneumococcus) if the infant is old enough
-Genetic testing for specific SCID-causing mutations
-Viral and bacterial cultures for suspected infections.
Differential Diagnosis: Other causes of recurrent infections in infancy:Transient hypogammaglobulinemia of infancy, DiGeorge syndrome (22q11.2 deletion), Wiskott-Aldrich syndrome, Ataxia-telangiectasia, other severe combined immunodeficiencies, acquired immunodeficiencies (e.g., HIV infection, though rare in neonates in India without specific risk factors).

Newborn Screening And Early Detection

Screening Programmes:
-Many developed countries have implemented SCID NBS programs using TREC analysis on dried blood spots collected at routine newborn screening
-TRECs are DNA circles formed during T-cell development
-their absence indicates a defect in T-cell maturation
-A positive screen (low TREC count) requires urgent confirmatory testing.
Importance Of Timeliness:
-Early detection through NBS is crucial
-Infants identified before symptom onset have significantly better outcomes with HSCT
-Delay in diagnosis leads to increased morbidity and mortality due to infections and potential damage to organs from infection.
Interpretation Of Results:
-A low TREC count on NBS is a screening indication, not a diagnosis
-It requires immediate follow-up with confirmatory laboratory testing: lymphocyte subset analysis to quantify T, B, and NK cells and genetic testing to identify the underlying mutation.

Protective Isolation And Management

Protective Isolation Measures:
-Strict protective isolation is paramount for infants with suspected or confirmed SCID
-This includes: placing the infant in a private room with positive pressure ventilation, strict hand hygiene for all caregivers, use of personal protective equipment (gowns, gloves, masks) by healthcare workers and visitors, avoiding contact with individuals who are ill, and limiting visitors
-Breast milk should be pasteurized if there is any risk of CMV transmission, or formula feeding may be preferred.
Antimicrobial Prophylaxis:
-Prophylactic antibiotics, antifungals (e.g., fluconazole), and antivirals (e.g., acyclovir) are often initiated empirically to prevent common opportunistic infections while awaiting diagnosis or treatment
-Pneumocystis jirovecii pneumonia (PCP) prophylaxis (e.g., trimethoprim-sulfamethoxazole) is critical.
Hematopoietic Stem Cell Transplantation Hsct:
-HSCT is the gold standard treatment for SCID
-Early HSCT (ideally before 3-6 months of age, and before any serious infections) offers the best chance of cure
-Matched sibling donors are preferred, followed by matched unrelated donors or haploidentical donors
-Gene therapy is an alternative for specific SCID subtypes where gene correction is feasible.
Supportive Care:
-Nutritional support is vital, as malabsorption and diarrhea are common
-Intravenous immunoglobulin (IVIG) replacement therapy may be used for B-cell defects to provide passive immunity and manage infections while awaiting definitive treatment
-Careful monitoring for any signs of infection is ongoing.

Key Points

Exam Focus:
-NBS for SCID relies on TREC analysis
-Low TRECs indicate a T-cell defect
-SCID infants lack both T and B cell function
-Clinical presentation is dominated by severe, recurrent infections
-HSCT is the definitive treatment
-timing is critical for survival
-Protective isolation prevents life-threatening infections.
Clinical Pearls:
-Always consider SCID in infants with recurrent severe infections, failure to thrive, and absent lymphoid tissue
-Absence of lymphadenopathy or tonsillar hypertrophy in an infant with severe infections is a major clue
-Never give live vaccines (e.g., rotavirus, oral polio, BCG) to infants with suspected or confirmed SCID.
Common Mistakes:
-Delaying confirmatory testing after a positive NBS TREC result
-Administering live vaccines to at-risk infants
-Misinterpreting normal lymphocyte counts without subset analysis
-Failing to implement strict protective isolation measures promptly.