Overview

Definition:
-Sickle cell disease (SCD) is a group of inherited red blood cell disorders characterized by abnormal hemoglobin (HbS)
-This leads to chronic hemolytic anemia, vaso-occlusion, and organ damage
-Health maintenance focuses on preventing serious complications like stroke and infection.
Epidemiology:
-SCD is the most common inherited blood disorder globally, with higher prevalence in individuals of African, Mediterranean, Middle Eastern, and Indian descent
-In India, sickle cell disease is prevalent in tribal populations and certain endemic regions, with varying genotypes and severity.
Clinical Significance:
-Effective health maintenance in SCD significantly reduces morbidity and mortality
-Early identification and consistent management of risks, particularly stroke and overwhelming post-splenectomy infection (OPSI), are crucial for improving long-term outcomes and quality of life for affected children.

Clinical Presentation

Symptoms:
-Chronic anemia presenting as pallor and fatigue
-Recurrent painful crises (vaso-occlusive crises)
-Increased susceptibility to infections, especially pneumococcal
-Delayed growth and puberty
-Organ-specific symptoms like acute chest syndrome, stroke, priapism, or splenic sequestration.
Signs:
-Pallor, jaundice
-Splenomegaly (early in life, often shrinks later)
-Hepatomegaly
-Cardiac murmurs due to anemia
-Signs of stroke (focal neurological deficits)
-Signs of infection (fever, respiratory distress).
Diagnostic Criteria:
-Diagnosis is typically made by newborn screening or laboratory evaluation
-Hemoglobin electrophoresis is the gold standard for identifying HbS and other hemoglobin variants
-Complete blood count (CBC) reveals anemia, reticulocytosis, and characteristic sickle-shaped red blood cells on peripheral smear.

Diagnostic Approach

History Taking:
-Detailed family history of anemia or blood disorders
-History of painful episodes, fevers, and previous hospitalizations
-Previous infections, blood transfusions, or stroke
-Current medications and adherence to prophylaxis
-Immunization status.
Physical Examination: Thorough physical examination focusing on signs of anemia, jaundice, organomegaly (spleen, liver), cardiovascular system, neurological assessment for focal deficits, and assessment of skin integrity to identify potential infection sites.
Investigations:
-Hemoglobin electrophoresis: Confirms diagnosis and genotype (HbSS, HbSC, HbS-beta-thalassemia)
-Complete blood count (CBC): Monitors anemia, reticulocyte count, and white blood cell count
-Renal and liver function tests: Assess organ function
-Urine analysis: Detects proteinuria and hematuria
-Echocardiogram: Evaluates cardiac function and pulmonary hypertension
-Imaging studies (MRI/CT): For suspected stroke or organ damage.
Differential Diagnosis:
-Other hemoglobinopathies (thalassemias, HbC disease)
-Autoimmune hemolytic anemia
-Sepsis with anemia
-Other causes of painful crises (e.g., osteomyelitis)
-Hereditary spherocytosis.

Management

Initial Management:
-For vaso-occlusive crisis: hydration, analgesia (opioids), oxygen if hypoxic, and treatment of precipitating factors (e.g., infection)
-For fever: aggressive evaluation for infection, prompt broad-spectrum antibiotics
-For acute chest syndrome: oxygen, antibiotics, pain control, consideration for exchange transfusion.
Medical Management:
-Penicillin prophylaxis: Recommended from 2 months of age until at least 5 years, or longer based on clinical assessment and splenic function
-Doses: typically 125 mg BID for <3 years, 250 mg BID for >3 years
-Hydroxyurea: Increases fetal hemoglobin (HbF), reducing pain crises and acute chest syndrome
-Monitor CBC, liver/renal function
-Regular blood transfusions: For severe anemia, stroke, or recurrent acute chest syndrome
-Exchange transfusion may be used for stroke or severe acute chest syndrome
-Pain management: NSAIDs, opioids (morphine, hydromorphone), patient-controlled analgesia (PCA).
Supportive Care:
-Nutritional support: Adequate caloric and fluid intake
-Genetic counseling for families
-Psychosocial support for patients and families
-Multidisciplinary care team including hematologist, pediatrician, social worker, and child life specialist
-Pain management strategies beyond pharmacotherapy: distraction, relaxation techniques
-Patient education regarding hydration, fever, and when to seek medical attention.
Prevention Strategies:
-Vaccinations: Pneumococcal conjugate vaccine (PCV13), pneumococcal polysaccharide vaccine (PPSV23), Haemophilus influenzae type b (Hib), meningococcal conjugate vaccine
-Annual influenza vaccination
-Regular dental check-ups
-Avoidance of dehydration and extreme temperatures
-Prompt recognition and treatment of fever.

Transcranial Doppler Screening

Purpose:
-Transcranial Doppler (TCD) ultrasonography is a non-invasive test used to assess the velocity of blood flow in the intracranial arteries
-It identifies children with sickle cell disease who are at increased risk of stroke.
Indications:
-Recommended for all children with sickle cell anemia (HbSS) and sickle cell-beta(0)-thalassemia between the ages of 2 and 16 years, typically starting at age 2
-TCD screening is also considered for other genotypes with high stroke risk.
Interpretation:
-Abnormal TCD results are defined by specific blood flow velocities, typically > 200 cm/s in the middle cerebral artery (MCA) or internal carotid artery (ICA), or > 170 cm/s in the anterior cerebral artery (ACA)
-Time-averaged mean velocity (TAMV) is used for standardized interpretation
-Conditional and abnormal TCD findings indicate increased stroke risk.
Management Of Abnormal Tcd:
-Children with abnormal TCD velocities are at high risk for ischemic stroke and should be considered for chronic blood transfusion therapy
-Transfusion is typically initiated with monthly packed red blood cell transfusions to maintain hemoglobin S levels below 30%
-Regular TCD follow-up is performed to monitor the effectiveness of transfusions and assess for normalization of velocities.
Follow Up Screening:
-Children with normal TCD velocities should be rescreened annually until age 16
-Children with conditional TCD velocities should be rescreened every 6 months and may benefit from close monitoring and lifestyle modifications
-Children with abnormal velocities receive chronic transfusions and are monitored with TCD every 3-6 months.

Complications

Early Complications:
-Vaso-occlusive crises (painful episodes)
-Acute chest syndrome
-Stroke (ischemic or hemorrhagic)
-Splenic sequestration
-Priapism
-Aplastic crisis.
Late Complications:
-Chronic organ damage: kidney disease (renal insufficiency, proteinuria), liver disease, pulmonary hypertension, cardiomyopathy
-Leg ulcers
-Osteomyelitis
-Cholelithiasis
-Retinopathy
-Avascular necrosis of bones
-Cognitive impairment.
Prevention Strategies:
-Consistent adherence to penicillin prophylaxis and immunizations is paramount for infection prevention
-Regular TCD screening and timely initiation of transfusions for stroke risk reduction
-Prompt management of painful crises and acute chest syndrome
-Use of hydroxyurea to reduce disease severity
-Genetic counseling and family support.

Prognosis

Factors Affecting Prognosis:
-Genotype (HbSS generally has worse prognosis than HbSC or HbS-beta-thalassemia trait)
-Presence and severity of complications (stroke, organ damage)
-Adherence to medical management and prophylaxis
-Access to comprehensive care and timely interventions.
Outcomes:
-With aggressive health maintenance, including penicillin prophylaxis, TCD screening, hydroxyurea, and judicious use of transfusions, the long-term outlook for children with sickle cell disease has significantly improved
-Lifespan has increased considerably.
Follow Up:
-Lifelong follow-up with a hematologist is essential
-Regular monitoring includes CBC, blood chemistries, urinalysis, and organ-specific assessments (e.g., echocardiography, renal function tests, ophthalmology exams)
-TCD screening continues until age 16 for most children, with ongoing risk assessment.

Key Points

Exam Focus:
-Understand the rationale and schedule for penicillin prophylaxis and TCD screening in children with sickle cell disease
-Recognize indications for hydroxyurea and blood transfusions
-Identify signs and management of acute complications like vaso-occlusive crisis and acute chest syndrome.
Clinical Pearls:
-Always start penicillin prophylaxis by 2 months of age
-TCD screening is crucial for primary stroke prevention from age 2
-Fever in a child with sickle cell disease is a medical emergency requiring prompt evaluation and broad-spectrum antibiotics
-Hydroxyurea is a cornerstone of chronic management for reducing disease burden.
Common Mistakes:
-Discontinuation of penicillin prophylaxis too early without adequate clinical assessment
-Delaying evaluation and treatment of fever
-Not performing or acting upon abnormal TCD findings
-Underestimating the pain severity in vaso-occlusive crises
-Inconsistent medication adherence by patients or caregivers.