Overview

Definition:
-Thyroid eye disease (TED), also known as Graves' ophthalmopathy (GO), is an autoimmune condition primarily affecting the orbit, characterized by inflammation and enlargement of the extraocular muscles and orbital fat
-In children, it is less common than in adults and often associated with Graves' disease.
Epidemiology:
-TED is rare in children, accounting for less than 5% of all TED cases
-It predominantly affects prepubertal and adolescent girls
-The incidence is significantly lower than in adults, with most pediatric cases linked to autoimmune thyroid disease, most commonly Graves' disease.
Clinical Significance:
-Prompt recognition and appropriate management of pediatric TED are crucial to prevent vision-threatening complications such as optic nerve compression, corneal ulceration, and strabismus, which can significantly impact a child's quality of life and visual development
-Early intervention improves outcomes.

Clinical Presentation

Symptoms:
-Proptosis or exophthalmos
-Eyelid retraction causing a staring appearance
-Diplopia (double vision), especially on upward gaze
-Periorbital edema
-Redness or injection of the conjunctiva
-Chemosis
-Pain or a feeling of fullness in the eyes
-Dry eyes or excessive tearing
-Blurred vision or decreased visual acuity
-Photophobia.
Signs:
-Proptosis/Exophthalmos as measured by Hertel exophthalmometer
-Eyelid retraction (Dalrymple's sign)
-Lid lag on downgaze (Von Graefe's sign)
-Infrequent blinking (Stellwag's sign)
-Limited extraocular muscle movement, leading to strabismus and diplopia
-Conjunctival injection and chemosis
-Optic nerve dysfunction may manifest as reduced visual acuity, afferent pupillary defect, or dyschromatopsia.
Diagnostic Criteria:
-Diagnosis is typically based on clinical findings in the presence of confirmed autoimmune thyroid disease (primarily Graves' disease)
-The EUGOGO (European Group on Graves' Orbitopathy) and R.I.A.C.H.I
-(Revised Activity Score in Childhood Graves' Disease) criteria can be adapted
-Key features include proptosis, eyelid retraction, diplopia, and evidence of orbital inflammation or congestion
-Radiographic confirmation (CT/MRI) may be needed to assess orbital involvement.

Diagnostic Approach

History Taking:
-Detailed history of onset and progression of eye symptoms
-History of known or suspected thyroid dysfunction (Graves' disease, Hashimoto's thyroiditis)
-Family history of autoimmune thyroid disease or TED
-Constitutional symptoms like weight loss, palpitations, tremors, heat intolerance
-Medications taken by the child
-Exposure to iodine or radiation.
Physical Examination:
-Comprehensive ophthalmological examination including visual acuity, visual fields, color vision, pupillary reflexes
-Palpation of the thyroid gland
-Measurement of exophthalmos using a Hertel exophthalmometer
-Assessment of eyelid retraction and lid lag
-Evaluation of ocular motility for limitations and diplopia
-Fundus examination to check for papilledema or optic disc pallor
-Slit-lamp examination of the conjunctiva and cornea.
Investigations:
-Thyroid function tests: TSH, free T4, free T3, TPO antibodies, TRAb (TSH receptor antibodies) to confirm or diagnose Graves' disease
-Orbital imaging: CT or MRI scans of the orbits can demonstrate extraocular muscle enlargement, orbital fat hypertrophy, and optic nerve sheath thickening, aiding in diagnosis and assessing disease severity and activity
-Visual evoked potentials (VEPs) may be used to assess optic nerve function.
Differential Diagnosis:
-Other causes of proptosis in children: orbital cellulitis, orbital tumors (e.g., rhabdomyosarcoma, optic glioma), orbital pseudotumor, neuroblastoma metastasis, and cavernous sinus thrombosis
-Differentiating TED requires correlating eye signs with thyroid status and orbital imaging findings.

Management

Initial Management:
-Control of hyperthyroidism is paramount
-Antithyroid medications (e.g., methimazole, propylthiouracil) are the mainstay
-Radioactive iodine therapy and thyroidectomy are generally deferred in active TED, especially with optic nerve compromise, due to potential exacerbation
-Smoking cessation is critical if the child is exposed to smoke
-Selenium supplementation may be considered in mild cases.
Medical Management:
-For active inflammatory TED: Corticosteroids (oral or intravenous) are the first-line treatment for moderate to severe active disease, especially with optic nerve compression
-Intravenous methylprednisolone pulses are often preferred
-Lubricating eye drops and ointments for dry eyes
-Prism correction for diplopia
-Management of underlying hyperthyroidism with antithyroid drugs to achieve euthyroid state
-Immunosuppressive agents (e.g., azathioprine, mycophenolate mofetil) may be used for refractory cases or steroid-sparing
-Benzodiazepines can help with anxiety.
Surgical Management:
-Surgical intervention is reserved for inactive, stable TED and is usually performed in a staged manner after the thyroid status is controlled and eye inflammation has subsided
-Surgical options include: Orbital decompression (to relieve proptosis and optic nerve compression), strabismus surgery (to correct diplopia), and eyelid surgery (to correct retraction).
Supportive Care:
-Psychosocial support for the child and family
-Regular ophthalmological and endocrinological follow-up
-Education regarding the chronic nature of the disease and adherence to treatment
-Head elevation at night may reduce periorbital edema
-Avoidance of irritants like dust and smoke
-Protective eyewear.

Complications

Early Complications:
-Optic nerve compression leading to vision loss
-Corneal ulceration and infection due to exposure keratitis
-Severe diplopia impacting daily activities
-Rapidly progressive inflammation.
Late Complications:
-Fibrosis of extraocular muscles causing permanent strabismus
-Persistent proptosis and eyelid retraction leading to disfigurement
-Dry eye syndrome and recurrent corneal abrasions
-Reduced visual acuity and field defects
-Thyroid-associated orbitopathy progression even after thyroid normalization.
Prevention Strategies:
-Early diagnosis and treatment of underlying Graves' disease
-Aggressive management of active TED with corticosteroids
-Strict control of thyroid hormone levels
-Smoking cessation for the patient and household members
-Judicious use of radioactive iodine therapy in the presence of active TED
-Prompt surgical intervention for optic nerve compression.

Prognosis

Factors Affecting Prognosis:
-Severity and activity of TED at diagnosis
-Presence of optic nerve involvement
-Age of onset (earlier onset may have better prognosis for thyroid normalization but worse orbital outcomes)
-Adherence to treatment
-Smoking status
-Control of thyroid status.
Outcomes:
-With appropriate management, visual acuity can be preserved in most children
-However, cosmetic deformities and some degree of motility impairment may persist
-Complete resolution of symptoms is not always achieved, and long-term management may be required
-Pediatric TED can have a more aggressive orbital course compared to adult cases.
Follow Up:
-Regular follow-up with pediatric endocrinology and ophthalmology is essential
-Monitoring of thyroid function tests, ocular motility, visual acuity, and orbital status
-Patients require lifelong monitoring for recurrence or progression of thyroid disease and its ocular manifestations.

Key Points

Exam Focus:
-Pediatric TED is rare, often associated with Graves' disease
-Key features: proptosis, eyelid retraction, diplopia
-Management targets both thyroid status and orbital inflammation
-Corticosteroids are first-line for active disease
-Surgery is for stable, inactive disease.
Clinical Pearls:
-Always consider thyroid dysfunction in children presenting with proptosis or diplopia
-Differentiate TED from other orbital pathologies
-Aggressive management in children is crucial to prevent long-term visual sequelae
-Recognize that even after achieving euthyroid status, orbital symptoms can persist or worsen.
Common Mistakes:
-Delaying diagnosis due to rarity
-Underestimating the severity of TED in children
-Inappropriately using radioactive iodine therapy in active TED
-Failing to manage both thyroid dysfunction and orbital inflammation concurrently
-Not performing a thorough ophthalmological examination.